Description:
MENKES SYNDROME
Repository
|
NIGMS Human Genetic Cell Repository
|
Subcollection |
Heritable Diseases |
Class |
Disorders of Metal Metabolism |
Cell Type
|
Fibroblast
|
Transformant
|
Untransformed
|
Race
|
White
|
Family Member
|
1
|
Relation to Proband
|
proband
|
Confirmation
|
Molecular characterization after cell line submission to CCR
|
Species
|
Homo sapiens
|
Common Name
|
Human
|
Remarks
|
|
Passage Frozen |
6 |
|
IDENTIFICATION OF SPECIES OF ORIGIN |
Species of Origin confirmed by LINE assay |
|
Remarks |
Fibroblasts exhibit elevated Cu levels; positive family history; similarly affected brother and cousin; abnormal metallothionein gene regulation in response to copper; culture shows qualitative changes in Mc1 mRNA |
Ho IC, Lee TC, Sodium arsenite enhances copper accumulation in human lung adenocarcinoma cells. Toxicol Sci47:176-80 1999 |
PubMed ID: 10220854 |
|
Yamaguchi Y, Heiny ME, Suzuki M, Gitlin JD, Biochemical characterization and intracellular localization of the Menkes disease protein. Proc Natl Acad Sci U S A93:14030-5 1996 |
PubMed ID: 8943055 |
|
Vulpe C, Levinson B, Whitney S, Packman S, Gitschier J, Isolation of a candidate gene for Menkes disease and evidence that it encodes a copper-transporting ATPase [published erratum appears in Nat Genet 1993 Mar;3(3):273] [see comments] Nat Genet3:7-13 1993 |
PubMed ID: 8490659 |
|
Leone A, Pavlakis GN, Hamer DH, Menkes' disease: abnormal metallothionein gene regulation in response to copper. Cell40:301-9 1985 |
PubMed ID: 3967294 |
|
LaBadie GU, Beratis NG, Price PM, Hirschhorn K, Studies of the copper-binding proteins in Menkes and normal cultured skin fibroblast lysates. J Cell Physiol106:173-8 1981 |
PubMed ID: 6783668 |
|
Beratis NG, Price P, Labadie G, Hirschhorn K, 64Cu metabolism in Menkes and normal cultured skin fibroblasts. Pediatr Res12:699-702 1978 |
PubMed ID: 673539 |
|
Chan WY, Garnica AD, Rennert OM, Cell culture studies of Menkes kinky hair disease. Clin Chim Acta88:495-507 1978 |
PubMed ID: 699339 |
|
Goka TJ, Stevenson RE, Hefferan PM, Howell RR, Menkes disease: a biochemical abnormality in cultured human fibroblasts. Proc Natl Acad Sci U S A73:604-6 1976 |
PubMed ID: 1061160 |
Passage Frozen |
6 |
Split Ratio |
1:6 |
Temperature |
37 C |
Percent CO2 |
5% |
Medium |
Eagle's Minimum Essential Medium with Earle's salts and non-essential amino acids with 2mM L-glutamine or equivalent |
Serum |
10% fetal bovine serum Not inactivated |
Substrate |
None specified |
Subcultivation Method |
trypsin-EDTA |
Supplement |
- |
|
|